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European Journal of Applied Sciences – Vol. 11, No. 1

Publication Date: January 25, 2023

DOI:10.14738/aivp.111.13891. Mangia, C. M. F., Toledo, M. D., Rossi, R., Nakano, E. Y., Carneluti, A., Kopelman, B. I., Carvalho, W. B., & Andrade, M. C. (2023).

Performance of Brazilian Pediatric Risk of Severity Model for Illness (Br PRISM) Compared to Pediatric Index of Mortality and

Pediatric Risk of Mortality 2. European Journal of Applied Sciences, Vol - 11(1). 287-302.

Services for Science and Education – United Kingdom

Performance of Brazilian Pediatric Risk of Severity Model for

Illness (Br PRISM) Compared to Pediatric Index of Mortality and

Pediatric Risk of Mortality 2

Mangia, C. M. F. MD, MSc, MBA, PhD.

Pediatric Critical Care Division, Escola Paulista de Medicina,

Universidade Federal de São Paulo, Brazil

Toledo, M. D., MD.

Pediatric Critical Care Division, Escola Paulista de Medicina,

Universidade Federal de São Paulo, Brazil

Rossi, R., MD.

Pediatric Critical Care Division, Escola Paulista de Medicina,

Universidade Federal de São Paulo, Brazil

Nakano, E. Y.,PhD.

Statistics Department, Universidade de Brasília, Brazil

Carneluti, A., MD.

Faculdade de Medicina, FMABC, Brazil

Kopelman, B. I., PhD.

Pediatrics Department Escola Paulista de Medicina,

Universidade Federal de São Paulo, Brazil

Carvalho, W. B., PhD.

Pediatric Critical Care Division, Universidade de São Paulo

Andrade, M. C., MD, MSc, PhD.

Pediatric Nephrology Division, Escola Paulista de Medicina,

Universidade Federal de São Paulo, Brazil

ABSTRACT

Introduction: The best prognosis score with which to evaluate high-risk patients

upon admission into pediatric intensive care is not well established in resource- limited settings. The objective of study was to formulate a risk-of-illness severity

model for pediatric mortality to be applied upon PICU admission in resource- limited settings. Methods: Our study was designed to develop an illness severity

index and a prognostic model for critically ill children. A prospective, observational

multicenter pilot study, performed between February 1995 and October 1999,

evaluated the variables, methodology and statistical techniques for the

development of a model. A single-center prospective cohort study, performed

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between November 1999 and October 2004, collected information from

consecutive admissions into the Pediatric Intensive Care Unit (PICU) at a high- complexity university, teaching, and reference hospital in São Paulo, Brazil. Results:

In the pilot study, 1,459 patients (a PICU mortality rate of 16%) were included, and

in the second study, 1,033 patients (a PICU mortality rate of 13.9% and a hospital

mortality rate of 6.9% after PICU discharge) were included. We used multivariable

regression to determine two probabilistic models; the first addressed survival and

the overall probability of death (hospital plus PICU deaths), and the second was

conditional (i.e., PICU death). An illness severity index stratified these probabilities

into three risk strata: low-, medium- and high-risk patients. In the final step, the

new death probabilities were estimated using a Bayesian adjustment. Conclusions:

The model estimates three probabilities (survival, death in the PICU and death in

the hospital after PICU discharge) stratified into three risk categories. To the best

of our knowledge, this is the first study using a Bayesian adjustment to determine a

prognosis and illness severity, and it should enable us to make therapeutic

adjustments and provide appropriate counseling for high-risk patients in resource- limited settings.

INTRODUCTION

Prognostication efforts are important steps towards understanding the effects of diseases,

medical interventions, and healthcare policies as determinants of outcomes. Mortality risk

models enable the evaluation of the healthcare system, management capacity and quality of

care and facilitate evidence-based decision-making and better resource allocation [1,2,3].

The outcome in intensive care depends on several factors associated with the patient in the first

24 hours after admission and the disease course during the intensive care stay. Severity scores

are usually comprised of two parts: a severity score, which is a number (in general, a high score

reflects a more severe condition), and a probability model, which is an equation that expresses

the probability of death in the hospital or intensive care unit (ICU) [3,4,5].

No consensus about the classification of score systems to be used in the ICU has been reached;

they could be used once or repeatedly over time. There are numerous examples of score

systems, but the main systems are scores based on abnormalities in the physiological variables

measured in the first 24 hours (APACHE, PRISM, PIM) or organ-specific scoring, in which the

main prognostic factors are the number and duration of multiple-organ failures (SOFA, PELOD).

The Brazilian healthcare system is a predominantly public enterprise with universal access for

all citizens. Over the past few years, as part of the Millennium Development Goals for the

reduction of child mortality, new pediatric intensive care units (PICUs) like those in other areas

of the world [6] have been introduced.In 1998, the Brazilian Ministry of Health suggested using

the Pediatric Risk of Mortality (PRISM) [7] score to assess the severity of illnesses and mortality

risks and evaluate PICU performance. Studies have reported that this score is not suited for

critically ill children in resource-limited settings [8], and it is well recognized that performance

scores are variable because the case mix, therapy and selection of patients admitted into the

PICU differ over time. Indeed, PRISM has been outdated for more than 10 years and,

consequently, is obsolete [1,3,4,5].

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Mangia, C. M. F., Toledo, M. D., Rossi, R., Nakano, E. Y., Carneluti, A., Kopelman, B. I., Carvalho, W. B., & Andrade, M. C. (2023). Performance of

Brazilian Pediatric Risk of Severity Model for Illness (Br PRISM) Compared to Pediatric Index of Mortality and Pediatric Risk of Mortality 2. European

Journal of Applied Sciences, Vol - 11(1). 287-302.

URL: http://dx.doi.org/10.14738/aivp.111.13891

Our main objective was to formulate a risk-of-illness severity model for pediatric mortality to

be applied upon PICU admission in resource-limited settings [3].

METHODS

The Brazilian Pediatric Risk of Severity Model for Illness (Br PRISM) study was developed in

two steps. The first study was a prospective, multicenter, 2 teaching hospitals and 1 private

hospital), cohort study performed between February 1995 and October 1999 and included

1,450 patients. This study evaluated the variables, methodology, and viability of performing a

multicenter study in Brazil and the statistical techniques required for developing a scoring

system and probability model. The second, a validation study, was a single-center, prospective,

observational cohort study performed between November 1999 and October 2004 and

included 1,100 consecutive patients admitted into the Hospital São Paulo from Universidade

Federal de São Paulo, Brazil. Hospital São Paulo, a resource for five million inhabitants, is a high- complexity hospital affiliated with the university teaching medical school. The hospital has 700

beds (80 pediatric) and receives 530,000 emergencies, 32,264 admissions and 163,305

surgeries per year. The pediatric intensive care unit (PICU) has 8 beds and admits medical and

surgical patients between the ages of 0 and 19 years. In the study period, we had 16 pediatric

intensive care residents each year. The medical staff included 2 physicians during the day, 1

physician at night and a total staff of 18 pediatric intensivists (including weekends). In addition,

the nurse-to-patient ratio was 1 nurse to each of 3 beds and one physiotherapist to 8 beds.

Sample Selection

All the consecutive admissions of patients under the age of 19 were analyzed, except the

following: a) patients with a PICU stay of less than 24 hours; b) patients admitted while

receiving continuous cardiopulmonary resuscitation without stable signs for at least 2 hours;

c) brain-dead patients admitted for organ donation. For those patients with multiple PICU

admissions during the same hospital stay, only the data from the first admission were analyzed.

Re-admissions were analyzed if they occurred more than 30 days after PICU discharge. To

determine the outcome, the patients were followed up until they were discharged from the

hospital. Any patients remaining in the hospital after October 31, 2004, were excluded from the

study because their status could not be assessed. The study was approved by the institutional

ethics committee, and parental consent was obtained in all cases.

Variable Selection:

The variables were selected based on our past experience with first study, clinical judgment,

interviews with the intensivists and score review and considered a wide range of citations on

the literature, such as the Pediatric Risk of Mortality II [7] and III [9], the Acute Physiology, Age,

and Chronic Health Evaluation III [10], the Simplified Acute Physiology Score II [11], Mortality

Probability Models II [12], the Pediatric Index of Mortality [13] and the Acute Physiology, Age,

Chronic Health Evaluation II [14]. All the data were collected by the main investigator.

The physiological variables that were eligible for analysis are as follows: the systolic blood

pressure, the heart rate, the respiratory rate, the axillary temperature, any pupillary reactions,

the coma status, diuresis, arterial gasometry, the PaO2/FiO2 ratio, glucose, potassium, sodium,

creatinine, urea, hemoglobin, hematocrit, platelet count, the white blood cell count, and the

prothrombin and activated partial thromboplastin times. The other, non-physiological,

variables are as follows: age, age group, gender, the in-hospital location before PICU admission,

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any comorbidities, the clinical or surgical status, the diagnosis by system and etiology (during

the first 24 hours), the use of vasoactive drugs, the use of external oxygen or mechanical

ventilation, the length of stay (LOS) before and after the PICU, the PICU LOS, the total length of

the hospital stay and any outcome data (the vital status in the PICU and upon hospital

discharge) [13,14,15,16,17,18].

The physiological variables were collected upon admission, and, if the laboratory had missed

any biochemical data, we recorded the worst value achieved in the first 24 hours according to

the strict definitions of the previously established variables (Appendix 1). When these values

were age-dependent, we used the range limits of the normal physiological values by age group.

We developed a comprehensive instruction manual, which described all the procedures that

led to the data collection and definition. This manual was based on the evidence in the literature

and included a full description of the study and strict definitions of the variables, their codes,

and, when applicable, their units and normal ranges according to the age group. The age group

was based on the recommendations of the Ministry of Health, which established the following

risk-specific age groups for Brazilian children: less than 12 months, between 12 and 59 months,

between 60 and 119 months, between 120 and 179 months and between 180 and 228 months

[19].

The data were collected in a clinical report form (CRF), the variables were codified, and the

internal quality of the data was checked before keyboarding into the ACCESS® database that

was specially created for this study. The program checked for any out-of-range data using a

logical error system and compiled a report regarding any inconsistent data for each patient.

The quality control of the database included double-keyboarding by two trained and

independent physicians. The first and second sets of keyboarding were compared to the CRF to

determine the reliability of the data from the first and second procedures. The reliability of the

data was compared to that of the CRF and the medical record. To determine the diagnostic

category after PICU admission, we developed a list of the ten major categories of clinical

diseases and nine major categories of surgical interventions. For each major category, we

developed a list of 124 etiology classes according to the age group and the epidemiology of the

pediatric diseases [9,11,12]. The same procedure was used for the categorization of the

comorbidities [15].

Statistical Analysis

The demographic data were represented as absolute numbers and percentages, and the

continuous variables were represented as medians and interquartile ranges. A p-value of less

than 0.05 was significant.

We used multivariable regression to determine two probabilistic models; the first addressed

the probability of death in the PICU, and the second was conditional (i.e., the probability of

death in the hospital after the PICU stay) [20,21,22].

We eliminated variables from the models by backward deletion. These two models produced a

of probabilities for each patient. The first element focuses on hospital survival, the second

focuses on death in the hospital after PICU discharge, and the third probability focuses on the

death probability during the PICU stay. Based on these three probabilities, we created a

severity index that stratifies patients from the worst (PICU death) to best (hospital survival)

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Mangia, C. M. F., Toledo, M. D., Rossi, R., Nakano, E. Y., Carneluti, A., Kopelman, B. I., Carvalho, W. B., & Andrade, M. C. (2023). Performance of

Brazilian Pediatric Risk of Severity Model for Illness (Br PRISM) Compared to Pediatric Index of Mortality and Pediatric Risk of Mortality 2. European

Journal of Applied Sciences, Vol - 11(1). 287-302.

URL: http://dx.doi.org/10.14738/aivp.111.13891

outcomes according to a previously published method [23,24]. The a priori probabilities of

model were: 10% (death in the PICU), 5% (death in the hospital after PICU stay) and 85%

(hospital survival) [23,24]. As a final step, the Bayesian method was applied to estimate the

new adjustment of probabilities (a posteriori) using the severity index. Statistical analysis was

performed using SPSS (version 11.0) and Excel 2000.

RESULTS

The variables were collected from 1,100 patients, 67 patients were excluded (37 patients were

discharged within 24 hours after PICU admission, 2 patients were still hospitalized at the end

of the study, 17 patients died within the first 24 hours after PICU admission, and 11 patients

were admitted into the PICU for organ donation after brain death). Following the exclusions,

1,033 patients were included in the development of the model. The patients’ characteristics are

summarized in Table 1. Comorbidities were present in 73.9% of the patients. The main

comorbidities were as follows: congenital cardiac disease (21.2%), chronic neurological

disease (10.6%), chronic renal disease (7.6%) and chronic pulmonary disease (6.2%).

Table 2 presents the logarithm of the first regression analysis, and Table 3 presents the log of

the second regression analysis.

The severity index (SI) was calculated using the following equation: SI = (21⁄2 +1)Pr(U) -

(21⁄2)Pr(H), where Pr(U) is the probability of dying in the PICU, and Pr(H) is probability of dying

in the hospital after the PICU stay (table 4). The cutoff value was £ 0.15 for the SI of the

survivors, 0.16 to 0.30 for hospital mortality after the PICU stay, and 3 0.30 for PICU mortality.

Next, we re-adjusted the probabilities using 3 severity classes based on the cutoff points of the

index (high, medium, or low probability of death). The index demonstrated good differentiation

among the 3 severity classes (p<0.001). The area under the ROC curve (AUC) for the survivors

(index £ 0.15) was good (0.821; 95% CI, 0,789 - 0,854). The cutoff point was 0.1564 (sensitivity,

0.738; 1-specificity, 0.265). The Hosmer-Lemeshow goodness-of-fit chi-squared value for the

survivors was 22.154 with 8 degrees of freedom (p=0.005).

The AUC for death in the PICU (index 3 0.30) was good (0.746; 95% CI, 0,676 - 0,817). The

cutoff point was 0.3058 (sensitivity, 0.674; 1-specificity, 0.324). The Hosmer-Lemeshow

goodness-of-fit chi-squared value for the deaths in the PICU was 9.300 with 8 degrees of

freedom (p=0.318). The a posteriori probabilities for each diagnostic category (hospital

survival, patient death in the hospital after the PICU stay and patient death during the PICU

stay) and the risk strata are presented in Table 5.

Br PRISM Compared to PIM and PIM 2

We compared the performance of Br PRISM to two scores with free access in the literature. The

Pediatric Index of Mortality (PIM; versions 1 and 2) met this criterion. The PIM and PIM 2 scores

were collected for 387 patients. The standardized mortality rate (SMR) for the PIM score was

2.464 (95% CI, 1.413 – 3.515), and the odds ratio was 0.56 (95% CI, 0.33 – 0.95); the SMR for

the PIM 2 score was 2.526 (95% CI, 1.366 – 3.687), and the odds ratio was 0.94 (95% CI, 0.57 –

1.57). The area under the ROC curve was 0.882 (95% CI, 0.846 - 0.913) for Br PRISM, 0.736

(95% CI, 0.689 - 0.7790) for PIM and 0.720 (95% CI, 0.672 - 0.764) for PIM 2. The pairwise

comparison of the ROC curves for Br PRISM vs. PIM and PIM2 showed a difference between the

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area under ROC curve (0.146; 95% CI, 0.054 - 0.238; p = 0.002). The areas of Br PRISM vs. PIM

2 were different (0.163; 95%, CI 0.066 - 0.260; p = 0.001). The areas of PIM vs. PIM 2 were also

different (0.017; 95% CI 0.044 -0.077; p = 0.591).

DISCUSSION

We undertook this study to develop an illness severity index and a prognostic risk model for

critically ill children that will be useful and relevant to middle-income environments. This

model is based on variables that are easily collected [25] at the bedside and includes well- defined [26] variables that are selected a priori. The investigators collecting the data were

blinded to the study objectives, and continuous, rigorous monitoring was done to eliminate the

possibility of missing [26,27] information to guarantee a high-quality database [28].

The laboratory variables were collected upon admission; however, when the sample was lost

or when technical problems arose during the processing of the samples by the laboratory, the

worst value during the first 24 hours was recorded [9]. We adopted this criterion because, in

our practice, the first sample was susceptible to loss (breakdown of the sample bottle, for

example), or there was a lack of the reagents with which to process the sample immediately or

during sampling [16].

We defined any admission that occurred after thirty days after PICU discharge as a new

admission. This admission would most likely be the result of a new clinical indication and,

therefore, unlikely to be due to an inappropriately early discharge [29]. Additionally, in our

medical practice, mortality in the PICU is an inadequate measure with which to evaluate the

outcomes of a critical disease. The inclusion of the hospital mortality after PICU discharge adds

a new element to the prediction and improves our knowledge regarding outcomes outside the

PICU, which may have a direct bearing on PICU care or the early discharge of unstable patients

[29].

By analyzing the regression models, we found that the overall survival depended more strongly

on the physiological variables. However, the biochemical abnormalities in the conditional

model were determinants of a major risk for dying in the hospital after PICU discharge.

The model supplied a vector of probabilities with three components (survival, PICU death and

hospital death after PICU stay). However, simultaneous interpretations of these data were

deemed to be too complex to explain to families and healthcare providers. Therefore, the

severity index simplifies the information because only one probability is necessary to explain

the gravity of each case [30,31].

The model described in this study don ́t need revised by new validation because the inclusion

of new patients in the database and the modification of its initial information the model will be

auto adjusted. The attraction of the Bayesian model is that it is a dynamic model and superior

to the information provided by the previous risk scores.

Comparing Br PRISM to the PIM and PIM 2 scores showed that the PIM and PIM 2 scores

overestimated the mortality in the high- and very high-risk bands and underestimated the

mortality in mild- and low-risk bands. The ROC curve analysis demonstrated that both had low

sensitivity and specificity in our population [32]. These observations could be explained by the

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Mangia, C. M. F., Toledo, M. D., Rossi, R., Nakano, E. Y., Carneluti, A., Kopelman, B. I., Carvalho, W. B., & Andrade, M. C. (2023). Performance of

Brazilian Pediatric Risk of Severity Model for Illness (Br PRISM) Compared to Pediatric Index of Mortality and Pediatric Risk of Mortality 2. European

Journal of Applied Sciences, Vol - 11(1). 287-302.

URL: http://dx.doi.org/10.14738/aivp.111.13891

fact that the PIM and PIM 2 scores have limitations in resource-limited settings. The

applicability of scores such as PIM and PIM 2 in our country is difficulted because of flaws in

these scores to assessment of the prognostics after PICU stay (like as death in the hospital stay

or hospital survival) and by differences of quality of care (including human, technological and

economic factors) rendered by PICU in resource limited settings compared to PICU of high- income settings where these scores were developed.

Our study has several limitations, including the fact that the final model was based on a single- center study. However, this option gave us control over data entry into the CRF, which ensured

data integrity (loss of sample and laboratory errors) and immediate mistake correction. For

example, in the pilot multicenter study, we observed that several variables with units different

from those that were standardized by the study were included in the database [20].

Another limitation relates to patient admission into the PICU. In resource-limited settings,

owing to the high demand for intensive-care beds, patients who should have been admitted into

the PICU earlier had stayed in other hospital settings, and, therefore, specific PICU treatments

were delayed [8].In these setting, patients requiring mechanical ventilation and patients after

high-risk surgery are priorities. This situation results in the baseline condition upon PICU

admission being worse than in high-income settings [32,33].

Parents also have difficulties on early recognition of the severity of diseases. Additionally, due

to socioeconomic reasons, a lack of transport or being transferred from other hospitals, some

patients may present late to emergency care [34]. This situation was represented in another

study as lead-time bias or the possibility that the patients may have had a higher-than- predicted mortality, which may generate some degree of error during scoring. However, this

situation is impossible to control [8]. In addition, the current model refers to a specific

population and will need to be used and validated in a new cohort similar to the reference

population before it can be used in a large-scale setting [16,35,36].

This model is the first pediatric model developed for resource-limited settings such as Brazil.

Brazil does not have a prognostic and severity model with which to examine the effect of

disease severity on patient admission into the PICU, after PICU stay and after Hospital stay. This

information would be useful when analyzing the costs (especially PICU and infirmary care

costs) to the Unified Health System (SUS) and the relative benefits to society. We believe that

the use of this model could improve the training of PICU teams by aiding in the development of

the skills necessary to discriminate between the severity categories of diseases, establish early

treatment strategies and minimize costs, mortality and sequelae.

Contributors

Mangia CMF wrote the methodology of this study, drafted study, carried out the cohort study,

all data collection, data typewrite, development of all steps of the database software, performed

the descriptive and inferential statistical analysis and wrote the manuscript. Nakano EY

performed the inferential and Bayesian statistical analysis. Carneluti A wrote the manuscript

and contributed with ideas and critical revision. Carvalho WB, Kopelman BI, Rossi R, Toledo

MD and Andrade MC contributed with ideas and critical revision, development of all steps of

this study. The paper was revised and approved by all contributors.

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Acknowledgements

We would kindly like to thank Pereira CAB, PhD (Bayesian analysis). Ms. Gucoff C for her

valuable work to develop the five versions of the database software and its updates. In addition,

we would kindly like to thank de Carvalho WB for his indispensable permission for the

accomplishment of this study in the PICU and to colleagues of all centers of pilot study.

Funding: None.

Conflict of Interest Statement: The authors declare that they have no conflict of interests.

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33. Van Keulen JG, Polderman KH, Gemke RJBJ. Reliability of PRISM and PIM scores in paediatric intensive care.

Arch Dis Child 2005; 90:211-214.

34. Higgins TL, McGee WT, Steingrub JS et al. Early indicators of prolonged intensive care unit stay: Impact of

illness and pre-intensive care unit lengh of stay. Crit Care Med 2003; 31:45-51.

35. Marik PE, Varon J. Severity scoring and oucome assessment. Crit Care Clin 1999; 15:633-46.

36. Le Gall JR. The use of severity scores in the intensive care unit. Intensive Care Med 2005; 31(12):1618-1623.

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Mangia, C. M. F., Toledo, M. D., Rossi, R., Nakano, E. Y., Carneluti, A., Kopelman, B. I., Carvalho, W. B., & Andrade, M. C. (2023). Performance of

Brazilian Pediatric Risk of Severity Model for Illness (Br PRISM) Compared to Pediatric Index of Mortality and Pediatric Risk of Mortality 2. European

Journal of Applied Sciences, Vol - 11(1). 287-302.

URL: http://dx.doi.org/10.14738/aivp.111.13891

Table1– Demographic characteristics of the patients.

N Frequency (%)

Number of patients 1033 100

Gender

Female 469 45.4

Male 564 54.6

Age group

< 12 months 447 43.3

12[―60 months 331 32.0

60[—120 months 150 14.5

120[— 180 months 88 8.5

180|—]228 months 17 1.6

Intra-hospital location before PICU admission

Emergency room 292 28.3

Ward 243 23.5

Intermediate care unit 106 10.26

Operating room 392 37.94

Major Categories of disease

Clinic 641 62.1

Surgical 392 37.9

Main Clinics Grupo Disease

Sepsis 190 18.4

Cardiovascular 102 9.9

Respiratory 221 21.4

LOS*, days (median, Q1 –Q3)†

LOS before PICU‡ 2.00 0 – 8

LOS PICU 5.00 2 – 9

LOS after PICU 9.00 3 –23

LOS Hospital 23.00 11 – 47

Outcome

Hospital Survival 818 79.2

Mortality

PICU mortality 144 13.9

Hospital mortality after PICU 71 6.9

Total mortality 215 20.8

*LOS: length of stay; † Q1, Q3: lower and upper interquartile range, respectively; ‡PICU: Pediatric intensive care

unit

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Table 2 – Variables for regression 1, the probability of death in PICU

with their estimated coefficients, standard error (SE), Wald statistic,

adjusted odds ratio, and 95% confidence intervals for the adjusted odds ratio.

B S.E. Wald df Sig. Exp(B) 95,0% C.I. for

EXP(B)

Lower Upper

Medical disease* 1,057 ,269 15,429 1 ,000 2,877 1,698 4,874

Comorbidities† 1,179 ,251 22,141 1 ,000 3,250 1,989 5,311

Hypotension‡ ,569 ,279 4,150 1 ,042 1,766 1,022 3,053

Pupil reaction‡ 2,006 ,500 16,096 1 ,000 7,431 2,789 19,795

Metabolic Coma § ,774 ,359 4,647 1 ,031 2,169 1,073 4,384

Hypoxemia || ,541 ,266 4,120 1 ,042 1,717 1,019 2,894

Mechanical ventilation¶ 1,014 ,286 12,593 1 ,000 2,757 1,575 4,828

Coagulopathy** ,850 ,240 12,489 1 ,000 2,339 1,460 3,747

Hyperglycemia †† ,789 ,245 10,399 1 ,001 2,201 1,363 3,555

Hyponatremia 1,047 ,291 12,913 1 ,000 2,848 1,609 5,040

Vasoactive drugs 1,059 ,240 19,531 1 ,000 2,884 1,803 4,613

Constant -5,603 ,436 165,364 1 ,000 ,004

β: coefficient; SE: standard error; Wald: statistic Wald; Sig: p value; CI 95%: confidence interval of 95%.

*Medical diseases: non-surgical patients; †comorbidities: congenital cardiophaties, oncologic diseases, chronic

kidney failure, chronic liver failure, genetic syndromes, AIDS; ‡systolic blood pressure (SBP): between 0 to 119

months £ 70mmHg and between 120 months to 180 months £ 90 mmHg. ‡ Pupil reaction: both fixed, miosis

bilateral and few reactions, pinpoint and no reactive, one fixed and one reactive.; §Glasgow metabolic: Glasgow

coma score for metabolic disease £ 10; ||Arterial oxygen saturation (Sat O2) < 90%; **APTT: 1.5 fold up to

reference value or > 52.5 sec; ††Glucose 3 150mg/dL; ‡‡Sodium £ 130mEq/L; Use of Mechanical ventilation¶ and

§§Vasoactive drugs.

†ATTP: Activated partial thromboplastin time

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Mangia, C. M. F., Toledo, M. D., Rossi, R., Nakano, E. Y., Carneluti, A., Kopelman, B. I., Carvalho, W. B., & Andrade, M. C. (2023). Performance of

Brazilian Pediatric Risk of Severity Model for Illness (Br PRISM) Compared to Pediatric Index of Mortality and Pediatric Risk of Mortality 2. European

Journal of Applied Sciences, Vol - 11(1). 287-302.

URL: http://dx.doi.org/10.14738/aivp.111.13891

Table 3–Conditional regression probability probability of death in the hospital

after PICU stay and their estimated coefficients, standard error (SE), Wald statistic,

adjusted odds ratio, and 95% confidence intervals for the adjusted odds ratio [EXP(B)].

B S.E. Wald Sig. Exp(B) 95,0% C.I. for EXP(B)

Lower Upper

Age group < 12 months* 1,203 ,305 15,537 ,000 3,330 1,831 6,056

Comorbidities† ,648 ,298 4,743 ,029 1,912 1,067 3,426

LOS before PICU‡ 1,660 ,324 26,305 ,000 5,258 2,788 9,914

Hyperthermia § -,876 ,350 6,255 ,012 ,417 ,210 ,827

Oliguria|| ,873 ,366 5,689 ,017 2,395 1,168 4,907

Metabolic Coma¶ 1,699 ,413 16,964 ,000 5,469 2,437 12,277

Coagulopathy /APTT ** ,715 ,302 5,610 ,018 2,045 1,131 3,697

Hypercalemia†† 1,701 ,433 15,403 ,000 5,477 2,343 12,804

Constant -4,206 ,370 129,219 ,000 ,015

Table 4 – Distribution of patients according to

severity index stratum and the area under ROC curve

Stratum Classification based in the Severity index and AUC

Diagnosis category Survivors

I* ≤ 0.1564

Low Risk

Hospital death

0.1564< I* <0.3058

Middle Risk

PICU death

I* ≥ 0.3058

High Risk

Total (n)

Survivors 604 146 68 818

Hospital death 34 14 23 71

PICU death 23 24 97 144

Total ( n) 661 184 188 1033

*Index (I) = (21⁄2 +1) Pr(U) - (21⁄2)Pr(H)

Table 5- Classification of severity according to its a posteriori probability.

Index Stratum Classification

Low Risk Middle Risk High Risk

Diagnosis category a priori The patient's probabilities after index (a posteriori)

Survival 85% 94% 85% 46%

Hospital death 5% 3.5% 5.6% 10.5%

PICU death 10% 2.4% 9.4% 43%

Interpretation:

a) If the patient is classified in the low index stratum, the vital status probabilities for each diagnosis category

(Survival; Hospital_death and PICU_death) are improved from 85%, 5% and 10% ( a priori) to 94%; 3.5% and

2.4% (posteriori), respectively;

b) If the patient is classified in the middle index stratum, the vital status of probabilities for each diagnosis

category (Survival; Hospital_death and PICU_death) are improved from 85%, 5% and 10% ( a priori) to 85%;

5.6% and 9.4% (posteriori), respectively;

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c) If the patient is classified in the high index stratum, the vital status of probabilities for each diagnosis category

(Survival; Hospital_death and PICU_death) are improved from 85%, 5% and 10% ( a priori) to 46%; 11% and

43% (posteriori), respectively;

Figure 1 - The area under the ROC curve (AUC) for survivors (BrPRISM index £ 0.15)

Figure 2 - The AUC for death in the PICU (BrPRISM index 3 0.30)

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Mangia, C. M. F., Toledo, M. D., Rossi, R., Nakano, E. Y., Carneluti, A., Kopelman, B. I., Carvalho, W. B., & Andrade, M. C. (2023). Performance of

Brazilian Pediatric Risk of Severity Model for Illness (Br PRISM) Compared to Pediatric Index of Mortality and Pediatric Risk of Mortality 2. European

Journal of Applied Sciences, Vol - 11(1). 287-302.

URL: http://dx.doi.org/10.14738/aivp.111.13891

Figure 3 - Comparison between ROC curves Br PRISM, PIM and PIM 2

APPENDIX 1

The values considered worst value in the model developing.

Variable Values

Age Group < 12 months

Medical No surgical patients

Comorbidity congenital cardiopathy, cancer, chronic kidney failure, chronic

liver failure, genetic syndrome, acquired immunodeficiency.

Pupil reactions Worst situation: both fixed, miosis bilateral and few reactions,

pinpoint and no reactive, one fixed and one reactive.

Glasgow coma scale Glasgow < 10 in the metabolic coma

Mechanical ventilation In the first 24 hr.

Vasoactive drugs In the first 24 hr.

Systolic blood pressure (mmHg)

< 12 months

12 to 59 months

60 to 119 months

120 to 179 months

> 180 months

£ 70 mmHg

£ 70 mmHg

£ 70 mmHg

£ 90 mmHg

£ 90 mmHg

Temperature (To. C) > 38 o

C

Diuresis (ml/kg/hr) < 1.0 ml/kg/hr.

Saturation O2 < 90%

Coagulation (sec) APTT (sec) 1.5 times up to reference value or > 52.5 sec.

Sodium (meq/l) £ 130

Potasium (meq/l) £3.0

Glucose (mg/dL) 3 150

LOS before PICU 3 8 days

The cutoff points were based in the literature review and univariate analysis of data

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APPENDIX 2

Sample Calculation of Score

Consider a child who is admitted to intensive care with the following data: age 16 months ( age

group < 12 months= no=0), severe sepsis (medical = yes=1), hasn ́t comorbities (no=0) ,

receiving vasoactive drugs (yes = 1), is ventilated immediately after admission (mechanical

ventilation = yes = 1), has a systolic blood pressure (SBP) of 63 mmHg ( SBP < 70mmHg

considering age group = yes=1 temperature of 38o.C ( Temp >38 o.C = yes=1), diuresis of 0.8

ml/kg/hr (diuresis £ 1.0ml/kg/hr = yes=1), ATTP of 105 sec. ( ATTP 3 52.5 sec = yes=1),

potassium of 2.0 mEq/L ( K < 3 mEq/L = yes=1), sodium of 129 mEq/L ( Na £ 130 mEq/L = yes

= 1), SatO2 of 89% ( Saturation arterial O2 < 90% = yes=1),normal pupils (no = 0) and glasgow

coma score > 10 ( no=0), waited in the emergency room for a bed in the ICU for 6 days (LOS

before PICU > 8 days = no= 0).

Using the coefficients in Table 2 and 3 we have final model derived from the first regression

and conditional regression, the Br PRISM logit for:

First Regression is

= (1.057*1) + (1.179*0) + (0.569*1) + (2.006*0) + (0.774*0) + (0.541*1) + (1.014*1) +

(0.850*1) +(0.789*1) + (1.047*1) + (1.059*1+ (- 5.603) = 1.323

Conditional Regression is

= (1.203*0) + (0.648*1) + (1.660*0) + (0.876*1) + (0.873*1) + (1.699*0) + (0.713*1) +

(1.701*1) + (-4.206) = -1.793

The logit should be converted to the predicted probability of death.

The predicted probability of death first regression)

= elogit/(1+elogit) =e 1.323/ (1+e 1.323) =0.78968

The predicted probability of death in the PICU (conditional regression)

= elogit/(1+elogit) = e -1.793/ (1+e -1.793) =0.142705

After this step, the probabilities should be used for calculating de index of severity-of- illness

= (21⁄2 +1) Pr(U) - (21⁄2) Pr(H)= [(21/2 +1) * 0.78968]-[(21⁄2) *0.142705= 0.65 (high risk index 3

0.3058 (table 4).

In the table 5, the high-risk patient is in the column 3 the a priori probability of death in PICU

was 10% and after adjustment the probability of death in PICU was estimated in 43% (a

posteriori probability). A priori probability for hospital death after PICU stay was 5% after

adjustment the probability is 10.5%. A priori probability for survival after hospital stay was

85% and a posteriori 46%